Odontogenic keratocyst: wolf in a sheep’s coat

Authors

  • Cherry Anilkumaar Roy Department of Otorhinolaryngology, Head and Neck Surgery, Bharati Vidyapeeth and Research Center, Pune, Maharashtra, India
  • Mishra Prasun Department of Otorhinolaryngology, Head and Neck Surgery, Bharati Vidyapeeth and Research Center, Pune, Maharashtra, India
  • Jeevan Galagali Department of Otorhinolaryngology, Head and Neck Surgery, Bharati Vidyapeeth and Research Center, Pune, Maharashtra, India
  • Chethana Ramesh Department of Otorhinolaryngology, Head and Neck Surgery, Bharati Vidyapeeth and Research Center, Pune, Maharashtra, India
  • Kiran Ray Department of Otorhinolaryngology, Head and Neck Surgery, Bharati Vidyapeeth and Research Center, Pune, Maharashtra, India
  • Rakhee Raghavan Department of Otorhinolaryngology, Head and Neck Surgery, Bharati Vidyapeeth and Research Center, Pune, Maharashtra, India
  • Anuja Ghoshal Department of Otorhinolaryngology, Head and Neck Surgery, Bharati Vidyapeeth and Research Center, Pune, Maharashtra, India

DOI:

https://doi.org/10.18203/issn.2454-5929.ijohns20253814

Keywords:

Maxilla, Recurrence, Odontogenic keratocysts

Abstract

Odontogenic keratocyst (OKC) is a benign yet locally aggressive odontogenic lesion with a high recurrence rate. Although more commonly found in the mandible, OKCs may rarely involve the maxilla, posing diagnostic and surgical challenges. We report the case of a 65-year-old female with a recurrent, painful swelling in the upper gingiva, radiologically presenting as a well-defined expansile lytic lesion in the maxilla. The cyst was surgically enucleated under general anesthesia, and histopathology confirmed the diagnosis of odontogenic keratocyst. The patient remained asymptomatic with no recurrence at five months follow-up. This case highlights the need for awareness of atypical presentations of OKC, the importance of histopathological confirmation, and the role of long-term follow-up to monitor for recurrence or malignant transformation.

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Published

2025-11-25

How to Cite

Roy, C. A., Prasun, M., Galagali, J., Ramesh, C., Ray, K., Raghavan, R., & Ghoshal, A. (2025). Odontogenic keratocyst: wolf in a sheep’s coat . International Journal of Otorhinolaryngology and Head and Neck Surgery, 11(6), 734–737. https://doi.org/10.18203/issn.2454-5929.ijohns20253814