Bilateral submandibular gland agenesis with bilateral parotid hypertrophy: a rare presentation

Authors

  • Rakhi Kumari Department of Otorhinolaryngology, Institute of Medical sciences, Banaras Hindu University, Varanasi-221005, India
  • Priyanko Chakraborty Department of Otorhinolaryngology, Institute of Medical sciences, Banaras Hindu University, Varanasi-221005, India
  • Sidharth Pradhan Department of Otorhinolaryngology, Institute of Medical sciences, Banaras Hindu University, Varanasi-221005, India
  • Purnima Joshi Department of Otorhinolaryngology, Institute of Medical sciences, Banaras Hindu University, Varanasi-221005, India
  • Rajiv Kumar Jain Department of Otorhinolaryngology, Institute of Medical sciences, Banaras Hindu University, Varanasi-221005, India

DOI:

https://doi.org/10.18203/issn.2454-5929.ijohns20162183

Keywords:

Submandibular aplasia, Parotid hypertrophy, Cheek swelling

Abstract

Recurrent laryngeal nerve injury and hypoparathyroidism are two of the much discussed major complications Bilateral submandibular gland aplasia associated with bilateral hypertrophy of parotid gland is one of the rarest case presentation. The enlargement of parotid gland is mostly due to a compensatory mechanism of submandibular aplasia. This case report describes a 45 year female presented with diffuse swelling over bilateral preauricular and infraauricular area. CECT of face confirmed diffuse bilateral parotid gland enlargement associated with absence of submandibular gland.

References

Haktanır A. CT and MR findings of bilateral submandibular gland aplasia associated with hypertrophied symmetrical sublingual glands herniated through mylohyoid defects. Dentomaxillofacial Radiology. 2012;41:79–83.

Khaladkar SM, Ayush M, Chaudhary K, Thakkar DK. Isolated unilateral Non -Syndromic non- familial hypoplastic Parotid gland: Case Report. International J Healthcare and Biomed Res. 2014;2(3):88-93.

Inan UU, Yilmaz MD, Demir Y, Degirmenci B, Ermis SS, Ozturk F. Characteristics of lacrimo-auriculo-dento-digital (LADD) syndrome: Case report of a family and literature review. Int J Pediatr Otorhinolaryngol. 2006;70:1307–14.

Haktanir A, Degirmenci B, Acar M, Albayrak R, Yucel A. CT findings of head and neck anomalies in lacrimo-auriculo-dento-digital (LADD) syndrome. Dentomaxillofac Radiol. 2005;34:102–5.

Singh P, Warnakulasuriya S. Aplasia of submandibular salivary glands associated with ectodermal dysplasia. J Oral Pathol Med. 2004;33:634–6.

Hollister DW, Klein SH, De Jager HJ, Lachman RS, Rimoin DL. The lacrimo-auriculo-dento-digital syndrome. J Pediatr 1973;83(3):438–44.

Hodgson TA, Shah R, Porter R. The investigation of major salivary gland agenesis: A case report. J Oral pathology; Pedeatric Dentistry. 2001;23:131-4.

Gangidi SR, Cunliffe D. Hyperpalstic sublingual gland in association with a congenitally missing ipsilateral submandibiular gland. Journal of Surgical Case Reports. 2011;9(5);1-3.

Srinivasan A, Moyer JS, Mukherji SK. Unilateral submandibular gland aplasia associated with ipsilateral sublingual gland hypertrophy. AJNR Am J Neuroradiol. 2006;27:2214–6.

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Published

2016-07-05

Issue

Vol. 2 No. 3 (2016): July-September 2016

Section

Case Reports